Abstract
Vasculopathy associated with neurofibromatosis type 1 (NF-1) can cause a spontaneous hemothorax, which is an uncommon but life-threatening complication of the disease. We report a case of recurrent rupture of intercostal artery aneurysms in an NF-1 patient. A 40-year-old man with NF-1 suffered from a right spontaneous hemothorax. The bleeding source was not identified by dynamic contrast-enhanced computed tomography (CT), so he was initially treated by conservative therapy. However, repeated contrast CT revealed aneurysms of the right 10th intercostal artery. They were successfully occluded by transcatheter arterial embolization (TAE). Seven months afterward, he presented with sudden lower back pain and was diagnosed with a contralateral spontaneous hemothorax due to a ruptured aneurysm of the left 12th intercostal artery. TAE was successfully performed.
| Original language | English |
|---|---|
| Pages (from-to) | 179-182 |
| Number of pages | 4 |
| Journal | General Thoracic and Cardiovascular Surgery |
| Volume | 60 |
| Issue number | 3 |
| DOIs | |
| Publication status | Published - Mar 2012 |
| Externally published | Yes |
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Keywords
- Embolization
- Intercostal artery aneurysm
- Neurofibromatosis
- Recurrence
- Spontaneous hemothorax
ASJC Scopus subject areas
- Cardiology and Cardiovascular Medicine
- Surgery
- Pulmonary and Respiratory Medicine
Cite this
Recurrent rupture of intercostal artery aneurysms in neurofibromatosis type 1. / Misao, Takahiko; Yoshikawa, Takeshi; Aoe, Motoi; Ueda, Yutaka; Yodoya, Mitsuko; Sakurai, Jun.
In: General Thoracic and Cardiovascular Surgery, Vol. 60, No. 3, 03.2012, p. 179-182.Research output: Contribution to journal › Article
}
TY - JOUR
T1 - Recurrent rupture of intercostal artery aneurysms in neurofibromatosis type 1
AU - Misao, Takahiko
AU - Yoshikawa, Takeshi
AU - Aoe, Motoi
AU - Ueda, Yutaka
AU - Yodoya, Mitsuko
AU - Sakurai, Jun
PY - 2012/3
Y1 - 2012/3
N2 - Vasculopathy associated with neurofibromatosis type 1 (NF-1) can cause a spontaneous hemothorax, which is an uncommon but life-threatening complication of the disease. We report a case of recurrent rupture of intercostal artery aneurysms in an NF-1 patient. A 40-year-old man with NF-1 suffered from a right spontaneous hemothorax. The bleeding source was not identified by dynamic contrast-enhanced computed tomography (CT), so he was initially treated by conservative therapy. However, repeated contrast CT revealed aneurysms of the right 10th intercostal artery. They were successfully occluded by transcatheter arterial embolization (TAE). Seven months afterward, he presented with sudden lower back pain and was diagnosed with a contralateral spontaneous hemothorax due to a ruptured aneurysm of the left 12th intercostal artery. TAE was successfully performed.
AB - Vasculopathy associated with neurofibromatosis type 1 (NF-1) can cause a spontaneous hemothorax, which is an uncommon but life-threatening complication of the disease. We report a case of recurrent rupture of intercostal artery aneurysms in an NF-1 patient. A 40-year-old man with NF-1 suffered from a right spontaneous hemothorax. The bleeding source was not identified by dynamic contrast-enhanced computed tomography (CT), so he was initially treated by conservative therapy. However, repeated contrast CT revealed aneurysms of the right 10th intercostal artery. They were successfully occluded by transcatheter arterial embolization (TAE). Seven months afterward, he presented with sudden lower back pain and was diagnosed with a contralateral spontaneous hemothorax due to a ruptured aneurysm of the left 12th intercostal artery. TAE was successfully performed.
KW - Embolization
KW - Intercostal artery aneurysm
KW - Neurofibromatosis
KW - Recurrence
KW - Spontaneous hemothorax
UR - http://www.scopus.com/inward/record.url?scp=84860772270&partnerID=8YFLogxK
UR - http://www.scopus.com/inward/citedby.url?scp=84860772270&partnerID=8YFLogxK
U2 - 10.1007/s11748-011-0806-0
DO - 10.1007/s11748-011-0806-0
M3 - Article
C2 - 22419191
AN - SCOPUS:84860772270
VL - 60
SP - 179
EP - 182
JO - General Thoracic and Cardiovascular Surgery
JF - General Thoracic and Cardiovascular Surgery
SN - 1863-6705
IS - 3
ER -