A case of paroxysmal kinesigenic dyskinesia with spastic paraparesis

Yasuyuki Ohta, Yasuhiro Manabe, C. Sasaki, M. Shiote, T. Hayashi, M. Shoji, Koji Abe

Research output: Contribution to journalArticle

Abstract

We report the first case of paroxysmal kinesigenic dyskinesia (PKD) with spastic paraparesis. A 17-year-old male began to show a dystonic posture in both his upper limbs when walking at age 12 years. Neurological examination revealed bilateral talipes cavus, spasticity in all extremities with general hyperreflexia and pathological reflexes. On starting to walk, he showed a dystonic posture in bilateral maniphalanx, wrists, elbows, and toes. Magnetic resonance imaging (MRI) revealed high T2-weighted signal intensity in bilateral pyramidal tract. Although the combination of pyramidal and the basal ganglia disorders is very rare, the present case suggests an inter-relation of the pyramidal and the basal ganglia systems.

Original languageEnglish
Pages (from-to)684-686
Number of pages3
JournalNeurological Research
Volume24
Issue number7
DOIs
Publication statusPublished - Oct 2002

Fingerprint

Spastic Paraparesis
Posture
Basal Ganglia Diseases
Abnormal Reflexes
Pyramidal Tracts
Neurologic Examination
Toes
Elbow
Basal Ganglia
Wrist
Upper Extremity
Walking
Reflex
Extremities
Magnetic Resonance Imaging
Familial paroxysmal dystonia
Talipes Cavus

Keywords

  • Paroxysmal kinesigenic dyskinesia
  • Spastic paraparesis

ASJC Scopus subject areas

  • Clinical Neurology
  • Neuroscience(all)

Cite this

A case of paroxysmal kinesigenic dyskinesia with spastic paraparesis. / Ohta, Yasuyuki; Manabe, Yasuhiro; Sasaki, C.; Shiote, M.; Hayashi, T.; Shoji, M.; Abe, Koji.

In: Neurological Research, Vol. 24, No. 7, 10.2002, p. 684-686.

Research output: Contribution to journalArticle

Ohta, Yasuyuki ; Manabe, Yasuhiro ; Sasaki, C. ; Shiote, M. ; Hayashi, T. ; Shoji, M. ; Abe, Koji. / A case of paroxysmal kinesigenic dyskinesia with spastic paraparesis. In: Neurological Research. 2002 ; Vol. 24, No. 7. pp. 684-686.
@article{2d78f29c4d5940748d7cf4e75cdddc46,
title = "A case of paroxysmal kinesigenic dyskinesia with spastic paraparesis",
abstract = "We report the first case of paroxysmal kinesigenic dyskinesia (PKD) with spastic paraparesis. A 17-year-old male began to show a dystonic posture in both his upper limbs when walking at age 12 years. Neurological examination revealed bilateral talipes cavus, spasticity in all extremities with general hyperreflexia and pathological reflexes. On starting to walk, he showed a dystonic posture in bilateral maniphalanx, wrists, elbows, and toes. Magnetic resonance imaging (MRI) revealed high T2-weighted signal intensity in bilateral pyramidal tract. Although the combination of pyramidal and the basal ganglia disorders is very rare, the present case suggests an inter-relation of the pyramidal and the basal ganglia systems.",
keywords = "Paroxysmal kinesigenic dyskinesia, Spastic paraparesis",
author = "Yasuyuki Ohta and Yasuhiro Manabe and C. Sasaki and M. Shiote and T. Hayashi and M. Shoji and Koji Abe",
year = "2002",
month = "10",
doi = "10.1179/016164102101200582",
language = "English",
volume = "24",
pages = "684--686",
journal = "Neurological Research",
issn = "0161-6412",
publisher = "Maney Publishing",
number = "7",

}

TY - JOUR

T1 - A case of paroxysmal kinesigenic dyskinesia with spastic paraparesis

AU - Ohta, Yasuyuki

AU - Manabe, Yasuhiro

AU - Sasaki, C.

AU - Shiote, M.

AU - Hayashi, T.

AU - Shoji, M.

AU - Abe, Koji

PY - 2002/10

Y1 - 2002/10

N2 - We report the first case of paroxysmal kinesigenic dyskinesia (PKD) with spastic paraparesis. A 17-year-old male began to show a dystonic posture in both his upper limbs when walking at age 12 years. Neurological examination revealed bilateral talipes cavus, spasticity in all extremities with general hyperreflexia and pathological reflexes. On starting to walk, he showed a dystonic posture in bilateral maniphalanx, wrists, elbows, and toes. Magnetic resonance imaging (MRI) revealed high T2-weighted signal intensity in bilateral pyramidal tract. Although the combination of pyramidal and the basal ganglia disorders is very rare, the present case suggests an inter-relation of the pyramidal and the basal ganglia systems.

AB - We report the first case of paroxysmal kinesigenic dyskinesia (PKD) with spastic paraparesis. A 17-year-old male began to show a dystonic posture in both his upper limbs when walking at age 12 years. Neurological examination revealed bilateral talipes cavus, spasticity in all extremities with general hyperreflexia and pathological reflexes. On starting to walk, he showed a dystonic posture in bilateral maniphalanx, wrists, elbows, and toes. Magnetic resonance imaging (MRI) revealed high T2-weighted signal intensity in bilateral pyramidal tract. Although the combination of pyramidal and the basal ganglia disorders is very rare, the present case suggests an inter-relation of the pyramidal and the basal ganglia systems.

KW - Paroxysmal kinesigenic dyskinesia

KW - Spastic paraparesis

UR - http://www.scopus.com/inward/record.url?scp=0036788632&partnerID=8YFLogxK

UR - http://www.scopus.com/inward/citedby.url?scp=0036788632&partnerID=8YFLogxK

U2 - 10.1179/016164102101200582

DO - 10.1179/016164102101200582

M3 - Article

C2 - 12392206

AN - SCOPUS:0036788632

VL - 24

SP - 684

EP - 686

JO - Neurological Research

JF - Neurological Research

SN - 0161-6412

IS - 7

ER -